The Role of neuroinflammation in Gaucher Disease

  • Research type

    Research Study

  • Full title

    The role of neuroinflammation in Gaucher Disease; assessment using MRI and PET imaging.

  • IRAS ID

    221128

  • Contact name

    Aimee Donald

  • Contact email

    aimee.donald@nhs.net

  • Sponsor organisation

    The University of Manchester

  • Duration of Study in the UK

    0 years, 2 months, 1 days

  • Research summary

    Gaucher Disease is a rare inherited disorder which causes build up of fatty material in cells predominantly in cells of the bone marrow. This results in enlargement of the spleen and liver, damage to the bone marrow (and therefore to bones) and in some patients, build up of fatty cells in the brain causing a progressive brain disease.

    Some patients with brain disease become symptomatic very early in life, they suffer developmental delay, swallowing difficulties and seizures leading to premature death. Other patients have similar symptoms but they develop more slowly over years or decades; it is very difficult to predict how a patient will progress when they first present. Conventional brain imaging techniques have failed to demonstrate any consistent abnormalities in these patients.
    Pathology studies in both humans and mice have demonstrated that specific areas in the brain become inflammed in these neurological forms of Gaucher Disease. We will use a novel imaging technique called Positron Emission Tomography (PET) to measure the contribution of this inflammation in correlation with clinical examination and neurocognitive function.
    We hope to learn more about the neuropathology which occurs in this disease and see if there is greater neuroinflammation in those patients with more severe disease which would suggest that this technique could be used to 1 - give more accurate prognosis to families; 2- measure disease activity 3- measure responses to novel therapies in clinical trials.

  • REC name

    North West - Haydock Research Ethics Committee

  • REC reference

    17/NW/0704

  • Date of REC Opinion

    21 Dec 2017

  • REC opinion

    Favourable Opinion