SERINE PROTEASES AND SERPINS IN DUCHENNE MUSCULAR DYSTROPHY

  • Research type

    Research Study

  • Full title

    SERINE PROTEASE AND SERPIN LEVELS AND ACTIVITY IN CHILDREN WITH DUCHENNE MUSCULAR DYSTROPHY

  • IRAS ID

    186555

  • Contact name

    Addolorata Pisconti

  • Contact email

    pisconti@liverpool.ac.uk

  • Sponsor organisation

    Alder Hey Children’s NHS Foundation Trust

  • Clinicaltrials.gov Identifier

    6, Protocol, internal version number

  • Duration of Study in the UK

    0 years, 11 months, 31 days

  • Research summary

    DMD is an X-linked genetic disorder caused by mutations in the dystrophin gene leading to progressive muscle weakness and reduced life expectancy as a result of muscle destruction, fibrosis and chronic inflammation. There is no effective treatment or cure for DMD. Biochemical markers currently used for diagnosis (such as Creatine Kinase) rapidly become unreliable as the patient loses muscle mass, and the only way to monitor disease progression at the molecular level is through invasive muscle histological analysis. Consequently, there is an urgent need for non-invasive biomarkers to monitor disease activity in the muscle, both to inform treatment decisions and to provide a platform for future research.

    We aim to understand whether: (i) there is a correlation between the levels of specific Serpins and their cognate enzymes in the muscle and the levels of the same quantities in the blood of children affected by DMD; (ii) protein levels and enzymatic activity of specific serine proteases can serve as blood biomarkers for DMD.

  • REC name

    North East - Newcastle & North Tyneside 2 Research Ethics Committee

  • REC reference

    15/NE/0279

  • Date of REC Opinion

    5 Oct 2015

  • REC opinion

    Further Information Favourable Opinion