Fine grained facial image analysis in Wolf-Hirschhorn syndrome

  • Research type

    Research Study

  • Full title

    Fine grained facial image analysis in Wolf-Hirschhorn syndrome

  • IRAS ID

    188638

  • Contact name

    Oliver Quarrell

  • Contact email

    oliver.quarrell@sch.nhs.uk

  • Sponsor organisation

    Sheffield Childrens Hospital

  • Duration of Study in the UK

    4 years, 9 months, 1 days

  • Research summary

    Wolf-Hirschhorn syndrome (WHS) is very a rare disorder which results from loss of genetic material from the tip of chromosome 4. We cannot see the individual genes down the microscope but they get wound up onto structures called chromosomes which we can see. We have two copies of our genetic material so the chromosomes are in pairs: one chromosome from each pair comes from the mother and one from the father. If genetic material is missing from the tip of chromosome 4 then WHS is diagnosed. Some children have a small amount of genetic material missing and some children have a larger amount missing. In some cases there may be additional material from another chromosome. We recognise WHS if babies/children have problems with growth, development and epilepsy. There are also characteristic facial features. We have measured these characteristic facial features in children/young people with classical WHS using 3-Dimensional photographic images. It has been suggested that there is a very small area, called the critical region, which is always missing. Routine genetic tests have improved so that we can detect very small amounts of material which are missing from chromosome 4 in much finer detail. We would like to study children who have a just a very small amount of genetic material missing from the tip of chromosome 4 especially if it does not include the typical region. We would like to combine this detailed genetic result with a detailed analysis of the facial features and compare the results of the 3-D image with our series of patients with classical WHS facial features.

  • REC name

    Yorkshire & The Humber - Leeds East Research Ethics Committee

  • REC reference

    16/YH/0216

  • Date of REC Opinion

    22 Aug 2016

  • REC opinion

    Further Information Favourable Opinion