Evaluate the ENPP1 Deficiency and Early-Onset form of ABCC6 Deficiency

  • Research type

    Research Study

  • Full title

    A Prospective Observational Study to Evaluate Disease Presentation and Progression in Subjects with ENPP1 Deficiency and the Early-Onset Form of ABCC6 Deficiency

  • IRAS ID

    302674

  • Contact name

    Amish Chinoy

  • Contact email

    amish.chinoy@mft.nhs.uk

  • Sponsor organisation

    Inozyme Pharma, Inc.

  • Clinicaltrials.gov Identifier

    NCT05050669

  • Duration of Study in the UK

    1 years, 9 months, 28 days

  • Research summary

    This observational study will enrol all eligible patients with ENPP1 Deficiency or the early-onset form of ABCC6 Deficiency who consent/assent to participate, to give approximately 30 patients from birth through adulthood (infant, child and adult populations). The study will prospectively gather information about the natural history of ENPP1 Deficiency and the early-onset form of ABCC6 Deficiency.

    ENPP1 Deficiency is a rare genetic disorder caused by a deficiency in the ENPP1 enzyme which regulates inorganic pyrophosphate (PPi) levels in plasma. PPi is essential to prevent soft tissue calcium deposits. Infants with ENPP1 Deficiency have high mortality in the first 6 months of life, and children and adults with ENPP1 Deficiency experience on-going risk for organ calcification and dysfunction, rickets, and softening of the bone in adulthood with severe bone and joint pain and fatigue, giving a poor quality of life and function. No targeted therapy exists for this disease.
    Similar to ENPP1 Deficiency, ABCC6 Deficiency is a disorder of pathological calcification that manifests in a spectrum of phenotypes. A rare form resembles the acute infantile form of ENPP1 Deficiency and has thus been called Generalized Arterial Calcification of Infancy type 2 (GACI 2). Diagnosis can occur during infancy prior to genetic confirmation where patients with early-onset form of ABCC6 Deficiency present with an acute calcification phenotype.

    This study will observe how the disease progresses through blood and urine tests, physical assessments, imaging, and other medical tests. The study is planned to run for about 22 months from start to finish. This study has 2 parts, a Screening Period with Baseline Visit for approximately up to 28 day followed by the Observation Period of between 12 and 22 months. Participants will continue to receive standard medical care from their regular doctor for their disorder while they are in this study.

  • REC name

    London - Brighton & Sussex Research Ethics Committee

  • REC reference

    21/LO/0882

  • Date of REC Opinion

    27 Apr 2022

  • REC opinion

    Further Information Favourable Opinion