Dietary management and outcome of patients with Citrin deficiency

  • Research type

    Research Study

  • Full title

    Dietary management, clinical status and outcome of patients with Citrin deficiency in the UK

  • IRAS ID

    233728

  • Contact name

    Anita MacDonald

  • Contact email

    anita.macdonald@nhs.net

  • Sponsor organisation

    Birmingham Women's and Children's Hospital

  • Duration of Study in the UK

    1 years, 0 months, 1 days

  • Research summary

    Citrin deficiency is a rare inherited metabolic condition which causes diverse clinical symptoms at any age from infancy to adulthood. It is treated by a special diet but liver transplant is an option for older patients with poor metabolic control. Optimal dietary treatment is unknown and dietary treatments are diverse. Sugar and carbohydrate restriction is commonly advised but protein and a special fat (medium chain triglyceride [MCT] oil) supplementation is sometimes given. In illness a dietary emergency feeding plan is recommended but there is no consensus about its composition. We have identified 29 UK patients with citrin deficiency from 9 UK centres. We would like to apply to collect retrospective data about medical history, diet therapy and clinical outcome of each patient to provide data to help standardise UK dietary approach to citrin deficiency management.

  • REC name

    West Midlands - Solihull Research Ethics Committee

  • REC reference

    17/WM/0410

  • Date of REC Opinion

    21 Dec 2017

  • REC opinion

    Further Information Favourable Opinion