BMN 270-201: Gene Therapy Study in Severe Haemophilia A Patients

  • Research type

    Research Study

  • Full title

    A Phase 1/2, Dose-Escalation Safety, Tolerability and Efficacy Study of BMN 270, an Adenovirus-Associated Virus Vector–Mediated Gene Transfer of Human Factor VIII in Patients with Severe Haemophilia A

  • IRAS ID

    173490

  • Contact name

    Emily Symington

  • Contact email

    emily.symington1@NHS.net

  • Sponsor organisation

    BioMarin Pharmaceutical Inc.

  • Eudract number

    2014-003880-38

  • Duration of Study in the UK

    6 years, 1 months, 1 days

  • Research summary

    This study is being conducted by Biomarin Pharmaceutical Inc. as an open label, dose escalation study in order to determine the safety and efficacy of BMN 270 (an Adeno-Associated Virus based gene therapy vector in participants with severe Haemophilia A.

    Haemophilia A (HA) is an X-linked recessive bleeding disorder that affects approximately 1 in 5,000 males. It is caused by deficiency in the activity of coagulation factor VIII (FVIII), which is essential to blood clotting. Severe HA is classified as FVIII activity less than 1% of wild type (< 1 IU/dL), moderate disease comprises 1-5% of wild type activity and the mild form is 5-40% activity. Clinical manifestations of severe HA are frequent spontaneous bleeding episodes, predominantly in joints and soft tissues, with a substantially increased risk of death from haemorrhage when the brain is involved. Haemophilia A is well suited for a gene replacement approach because clinical manifestations are attributable to the lack of a single gene product (FVIII) that circulates in minute amounts (200 ng/ml) in the plasma.

    This is the first study to determine whether the treatment is safe at different dose levels and also to determine the dose at which BMN 270 may be sufficient to have a positive effect on participant’s Haemophilia A. BMN 270 offers the potential of disease modification by stimulating continuous endogenous production of FVIII levels following a single intravenous administration and is designed to achieve stable, potentially life-long expression of active hFVIII in the blood.

  • REC name

    South Central - Oxford A Research Ethics Committee

  • REC reference

    15/SC/0242

  • Date of REC Opinion

    2 Jun 2015

  • REC opinion

    Further Information Favourable Opinion