A Placebo-controlled study of Maralixibat in Subjects with PFIC

  • Research type

    Research Study

  • Full title

    MRX-502: Randomized Double-blind Placebo-controlled Phase 3 Study to Evaluate the Efficacy and Safety of Maralixibat in the Treatment of Subjects with Progressive Familial Intrahepatic Cholestasis (PFIC) – MARCH-PFIC

  • IRAS ID

    266069

  • Contact name

    Richard Thompson

  • Contact email

    richard.j.thompson@kcl.ac.uk

  • Eudract number

    2019-001211-22

  • Clinicaltrials.gov Identifier

    NCT03905330

  • Clinicaltrials.gov Identifier

    119916, IND

  • Duration of Study in the UK

    1 years, 10 months, 17 days

  • Research summary

    Summary of Research

    Progressive familial intrahepatic cholestasis (PFIC) is a rare liver disease that primarily affects children. PFIC taken word for word means:
    Progressive: tending to get worse over time;
    Familial: passed down to a child from the parents by way of the genes;
    Intrahepatic: involves disease inside the liver;
    Cholestasis: means poor bile flow and retention of substances in the liver that would normally be excreted into bile.
    PFIC is associated with short life expectancy and devastating consequences on patients’ quality of life. There is currently no approved treatment for PFIC and available medical approaches have limited efficacy.
    The proposed MARCH study is a multicentre, randomised, double blind, placebo controlled study which is to evaluate the efficacy and safety of study medicine called Maralixibat.
    Maralixibat is an investigational medicine (not yet approved by regulatory authorities) which will be given to patients twice a day in the form of oral solution. If the study medicine works as expected, it may help to reduce patients’ PFIC symptoms and pruritus (itching).
    Patients between ≥12 months and < 18 years of age with confirmed PFIC diagnosis, who meet all study eligibility criteria can participate in the study.
    Patient’s participation will last for approx. 33 weeks and will consist of 4 parts: screening period (up to 6 weeks), Dose Escalation period (4–6 weeks), Stable Dosing period (20–22 weeks) and Safety Follow-up period. Patients will be required to come to the study centre approx. 10 times. Additionally patients will be contacted via phone or email to check on how they are feeling.
    Patients will be randomised in a 1:1 ratio to the maralixibat or placebo (look alike treatment without active ingredient) treatment groups.
    During the study patients will undergo assessments which will include blood, urine tests, electrocardiogram (ECG), liver ultrasound and questionnaires.

    Summary of Results

    Maralixibat demonstrated statistically significant and clinically meaningful improvements in pruritus severity and serum bile acids in the primary and Progressive Familial Intrahepatic Cholestasis (PFIC) cohorts. Improvements in exploratory endpoints including direct bilirubin, total bilirubin, sleep, fatigue, and growth (weight z-score) were demonstrated in the PFIC cohort participants who received maralixibat. These improvements were all statistically significantly different from placebo in favor of maralixibat. In addition, maralixibat was shown to be well tolerated and demonstrated an acceptable safety profile; the most common treatment emergent Adverse Events in this study were gastrointestinal related, in line with the known mechanism of action. Taken together, the efficacy and safety findings from this study support an overall favorable benefit/risk assessment for maralixibat.

  • REC name

    London - Hampstead Research Ethics Committee

  • REC reference

    19/LO/1428

  • Date of REC Opinion

    29 Oct 2019

  • REC opinion

    Further Information Favourable Opinion